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Orthodontic and dentofacial orthopedic treatments in patients with ectodermal dysplasia: a systematic review

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dc.contributor.authorCerezo-Cayuelas, Marina
dc.contributor.authorPérez-Silva, Amparo
dc.contributor.authorSerna-Muñoz, Clara
dc.contributor.authorVicente, Ascensión
dc.contributor.authorMartínez Beneyto, Yolanda
dc.contributor.authorCabello-Malagón, Inmaculada
dc.contributor.authorOrtiz Ruiz, Antonio José
dc.contributor.departmentDermatología, Estomatología, Radiología y Medicina Física
dc.date.accessioned2024-06-19T11:05:29Z
dc.date.available2024-06-19T11:05:29Z
dc.date.issued2022-10-17
dc.description© The Author(s) 2022. This manuscript version is made available under the CC-BY 4.0 license http://creativecommons.org/licenses/by/4.0/ This document is the Published version of a Published Work that appeared in final form in Orphanet Journal of Rare Diseases. To access the final edited and published work see https://doi.org/10.1186/s13023-022-02533-0
dc.description.abstractObjective The objective of this systematic review was to determine the orthodontic and dentofacial orthopedic treatments carried out in patients with ectodermal dysplasia to facilitate functional and aesthetic rehabilitation. Methods The systematic review was conducted in accordance with the Preferred Reporting Items for Systematic Reviews and Meta-analysis statement. We systematically searched PubMed, Web of Science, Scopus, Scielo, LILACS, EBSCOhost and Embase databases up to 6 January 2022. We included articles describing patients with any type of ectodermal dysplasia who received orthodontic or dentofacial orthopedic treatment to facilitate functional and aesthetic oral rehabilitation. The search was not restricted by language or year of publication. The quality of the studies was assessed using the Joanna Briggs Institute Quality Assessment Scale of the University of Adelaide for case series and case reports. The review was registered at the University of York Centre for reviews (CRD42021288030). Results Of the initial 403 studies found, 29 met the inclusion criteria. After applying the quality scale, 23 were left for review—21 case reports and 2 case series. The initial age of patients ranged from 34 months to 24 years. Thirteen studies were on hypohidrotic and/or anhidrotic ectodermal dysplasia, of which two were X-chromosome linked. In one study, the patient had Wiktop syndrome, and in nine the type of ectodermal dysplasia was not specified. The duration of treatment was 7 weeks to 10 years. The treatments described were: fixed orthodontic appliances or simple acrylic plates designed for tooth movement, including leveling and aligning, closing of diastemata, retraction of impacted teeth in the dental arch; clear aligners; fixed and/or removable appliances for the correction of skeletal and/or dentoalveolar relationships; palatal expanders in combination with face masks for orthopedic traction of the maxilla; and orthognathic surgery. Only three studies provided cephalometric data. Conclusion The level of evidence of the articles reviewed was low and most orthopedic and dentofacial orthodontic treatments described were focused on correcting dental malpositioning and jaw asymmetries and not on stimulating growth from an early age. Studies with greater scientific evidence are needed to determine the best treatment for these patients.es
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dc.format.extent18es
dc.identifier.citationOrphanet Journal of Rare Diseases, 2022, Vol. 17, N. 1, 376
dc.identifier.doihttps://doi.org/10.1186/s13023-022-02533-0
dc.identifier.issnElectronic: 1750-1172
dc.identifier.urihttp://hdl.handle.net/10201/142443
dc.languageenges
dc.publisherBMC
dc.relationSin financiación externa a la Universidades
dc.relation.publisherversionhttps://ojrd.biomedcentral.com/articles/10.1186/s13023-022-02533-0
dc.rightsinfo:eu-repo/semantics/openAccesses
dc.rightsAtribución 4.0 Internacional*
dc.rights.urihttp://creativecommons.org/licenses/by/4.0/*
dc.subjectEctodermal dysplasiaes
dc.subjectOrthodontic treatmentes
dc.subjectDentofacial orthopedic treatmentes
dc.subjectAnhidrotic ectodermal dysplasiaes
dc.subjectHidrotic ectodermal dysplasiaes
dc.subjectHypohidrotic ectodermal dysplasiaes
dc.subjectAnodontiaes
dc.subjectHypodontiaes
dc.subjectMaxillary atrophyes
dc.titleOrthodontic and dentofacial orthopedic treatments in patients with ectodermal dysplasia: a systematic reviewes
dc.typeinfo:eu-repo/semantics/articlees
dspace.entity.typePublicationes
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